Multicystic biliary hamartoma (MCBH) is a very rare hamartomatous cystic nodule of the liver, which has recently been described as a new entity of a hepatic nodular lesion. We report a unique case of MCBH with a review of the literatures. A hepatic multicystic mass of segment 3 was detected in a 52-year-old male by abdominal computed tomography, and resection of this lesion was performed. Macroscopic examination revealed a 2.7×2.0 cm nodular mass with a multicystic honeycomb cut surface. Histologically, this lesion consisted of multiple dilated cystic ducts lined by biliary type epithelial cells, periductal glands and connective tissue, which included small amounts of hepatic parenchyma and blood vessels. Recognition of this unusual lesion is essential to avoid confusion with other cystic tumors of the liver, and to learn more about its natural history and response to treatment.

Citations

Citations to this article as recorded by  

• Technical Considerations in EEG Source Imaging
  Benjamin H. Brinkmann
  Journal of Clinical Neurophysiology.2024; 41(1): 2.     CrossRef
• A Case of Multicystic Biliary Hamartoma with a Marked Peribiliary Gland Component Successfully Treated by Purely Laparoscopic Anatomical Liver Resection
  Keita Kai, Takao Ide, Tomokazu Tanaka, Kumpei Yukimoto, Hiroyuki Irie, Hirokazu Noshiro, Shinichi Aishima
  Journal of Gastrointestinal Cancer.2023; 54(3): 996.     CrossRef
• Characteristics of multicystic biliary hamartoma: A case report
  Jia Lian, Lixia Sun, Yankai Yang, Jun Li, Ye Zhang, Guiqiu Liu, Weijuan Hu
  Frontiers in Surgery.2023;[Epub]     CrossRef
• Hamartoma multiquístico de vías biliares
  Victoria Carmona, Iago Justo, Yolanda Rodríguez-Gil, Alberto Marcacuzco, Carmelo Loinaz, Carlos Jiménez
  Cirugía Española.2022; 100(12): 800.     CrossRef
• Multicystic Biliary Hamartoma With Xanthogranulomatous Inflammation on 18F-FDG PET/CT
  Nahomi Shono, Yoichi Otomi, Hideki Otsuka, Takayoshi Shinya, Masafumi Harada
  Clinical Nuclear Medicine.2022; 47(10): 882.     CrossRef
• Intrahepatic multicystic biliary hamartoma: A case report
  Chen-Yu Wang, Fu-Yang Shi, Wei-Feng Huang, Yan Tang, Ting Li, Guo-Lin He
  World Journal of Clinical Cases.2022; 10(26): 9361.     CrossRef
• A Case of Multicystic Biliary Hamartoma Treated with Left Medial Sectionectomy
  Naomi KUROKI, Tomoaki TANAKA, Takanobu SUGASE, Syoji TANIGUCHI, Takashi GOTO, Rintaro KOGA, Takumi KIWAKI, Hiroyuki TANAKA
  Nihon Rinsho Geka Gakkai Zasshi (Journal of Japan Surgical Association).2022; 83(2): 395.     CrossRef
• Multicystic biliary hamartoma
  Victoria Carmona, Iago Justo, Yolanda Rodríguez-Gil, Alberto Marcacuzco, Carmelo Loinaz, Carlos Jiménez
  Cirugía Española (English Edition).2022; 100(12): 800.     CrossRef
• Case Report: Incidentally Discovered a Rare Cystic Lesion of Liver: Multicystic Biliary Hamartoma
  Wentao Mu, Peng Su, Shanglei Ning
  Pathology and Oncology Research.2021;[Epub]     CrossRef
• Bile Duct Hamartoma Mimicking Liver Metastasis in Suspected Porcelain Gallbladder: a Case Report
  Gautham Krishnamurthy, Harjeet Singh, Sravya Deepika Ganti, Ganga Ram Verma
  Journal of Gastrointestinal Cancer.2019; 50(4): 1022.     CrossRef
• A variant of multicystic biliary hamartoma presenting as an intrahepatic cystic neoplasm
  Tetsuro Tominaga, Takafumi Abo, Naoe Kinoshita, Tomonori Murakami, Yasunori Sato, Yasuni Nakanuma, Kenich Harada, Junichi Masuda, Takeshi Nagayasu, Atsushi Nanashima
  Clinical Journal of Gastroenterology.2015; 8(3): 162.     CrossRef
• Hamartoma biliar multiquístico intrahepático: presentación de un caso clínico
  María Jezabel Fernández-Carrión, Ricardo Robles Campos, Asunción López Conesa, Roberto Brusadín, Pascual Parrilla Paricio
  Cirugía Española.2015; 93(9): e103.     CrossRef
• Intrahepatic Multicystic Biliary Hamartoma: Presentation of a Case Report
  María Jezabel Fernández-Carrión, Ricardo Robles Campos, Asunción López Conesa, Roberto Brusadín, Pascual Parrilla Paricio
  Cirugía Española (English Edition).2015; 93(9): e103.     CrossRef
• Multicystic biliary hamartoma: A report of a rare entity and a review of the literature
  Rachel E. Beard, Eric U. Yee, Koenraad J. Mortele, Khalid Khwaja
  International Journal of Surgery Case Reports.2014; 5(12): 919.     CrossRef
• Multicystic biliary hamartoma mimicking intrahepatic cholangiocarcinoma: report of a case
  Tomoaki Yoh, Ryuji Okamura, Hiroyuki Nakayama, Xue Lin, Yuya Nakamura, Tatsushi Kato
  Clinical Journal of Gastroenterology.2014; 7(5): 418.     CrossRef

Citations

Citations to this article as recorded by  

• Simple mucinous cyst: another potential cancer precursor in the pancreas? Case report with molecular characterization and systematic review of the literature
  Anna Caterina Milanetto, Alice Sabrina Tonello, Giovanni Valotto, Giada Munari, Claudio Luchini, Matteo Fassan, Claudio Pasquali
  Virchows Archiv.2021; 479(1): 179.     CrossRef
• Mucinous Non-neoplastic Cyst of the Pancreas
  Jun Hyung Kim, Dong Eun Park, Keum Ha Choi
  The Korean Journal of Gastroenterology.2019; 73(4): 235.     CrossRef
• Mucinous nonneoplastic cyst of the pancreas: CT and MRI appearances
  Kousei Ishigami, Akihiro Nishie, Naoki Mochidome, Yoshiki Asayama, Yasuhiro Ushijima, Daisuke Kakihara, Daisuke Okamoto, Nobuhiro Fujita, Takao Ohtsuka, Yoshihiro Miyasaka, Tomoyuki Hida, Tomoharu Yoshizumi, Hiroshi Honda
  Abdominal Radiology.2017; 42(12): 2827.     CrossRef
• Pathologic Evaluation and Reporting of Intraductal Papillary Mucinous Neoplasms of the Pancreas and Other Tumoral Intraepithelial Neoplasms of Pancreatobiliary Tract
  Volkan Adsay, Mari Mino-Kenudson, Toru Furukawa, Olca Basturk, Giuseppe Zamboni, Giovanni Marchegiani, Claudio Bassi, Roberto Salvia, Giuseppe Malleo, Salvatore Paiella, Christopher L. Wolfgang, Hanno Matthaei, G. Johan Offerhaus, Mustapha Adham, Marco J.
  Annals of Surgery.2016; 263(1): 162.     CrossRef
• Rare Nonneoplastic Cysts of Pancreas
  Yeon Suk Kim, Jae Hee Cho
  Clinical Endoscopy.2015; 48(1): 31.     CrossRef